慢性肉芽肿性疾病
活性氧
微生物群
NADPH氧化酶
表型
生物
免疫系统
原发性免疫缺陷
免疫
结肠炎
免疫学
遗传学
基因
作者
Zohreh Mansoori Moghadam,Bei Zhao,Céline Raynaud,Valentina Strohmeier,Jana Neuber,Anne Kathrin Lößlein,Sonia Qureshi,Vitka Gres,Tara Ziegelbauer,Sebastian Baasch,Christoph Schell,Klaus Warnatz,Naohiro Inohara,Gabriel Núñez,Thomas Clavel,Stephan P. Rosshart,Julia Kolter,Philipp Henneke
出处
期刊:Blood
[Elsevier BV]
日期:2025-05-01
卷期号:145 (18): 2025-2040
被引量:6
标识
DOI:10.1182/blood.2024025240
摘要
The controlled development of cellular intestinal immunity in the face of dynamic microbiota emergence constitutes a major challenge in very early life and is a bottleneck for sustained growth and well-being. Early-onset inflammatory bowel disease (IBD) represents an extreme disturbance of intestinal immunity. It is a hallmark and often the first manifestation of chronic granulomatous disease (CGD), caused by inborn defects in the nicotinamide adenine dinucleotide phosphate oxidase 2 (NOX2) in phagocytes and thus the failure to produce reactive oxygen species (ROS). However, in contrast to the known role of ROS in antimicrobial defense, the mechanisms underlying intestinal immunopathology in CGD remain enigmatic. This is partly due to the incomplete recapitulation of the CGD-IBD phenotype in established mouse models. We found that mice deficient in the NOX2 subunits p47phox or gp91phox showed similar baseline disturbances in lamina propria macrophage differentiation but responded differently to chemically induced colitis. Although p47phox- and gp91phox-deficient mice differed markedly in microbiota composition, crossfostering failed to equalize discrepant IBD phenotypes and microbiota, pointing at extremely early and functionally important microbiota fixation under specific pathogen-free housing conditions. In contrast, neonatal acquisition of a complex wild-mouse microbiota triggered spontaneous IBD, granuloma formation, and secondary sepsis with intestinal pathogens in both NOX2-deficient mouse lines, which was in part dependent on NOX2 in intestinal macrophages. Thus, in experimental CGD, the aberrant development of tissue immunity and microbiota are closely intertwined immediately after birth.
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