Trio-based exome sequencing reveals a high rate of the de novo variants in intellectual disability

智力残疾 外显子组测序 遗传诊断 队列 遗传学 DNA测序 外显子组 人口 生物 遗传异质性 医学 基因 突变 内科学 表型 环境卫生
作者
Alejandro Brea‐Fernández,Míriam Álvarez-Barona,Jorge Amigo,María Tubío-Fungueiriño,Pilar Caamaño,Montse Fernández‐Prieto,Francisco Barros,Silvia De Rubeis,Joseph D. Buxbaum,Ángel Carracedo
出处
期刊:European Journal of Human Genetics [Springer Nature]
卷期号:30 (8): 938-945 被引量:34
标识
DOI:10.1038/s41431-022-01087-w
摘要

Intellectual disability (ID), a neurodevelopmental disorder affecting 1-3% of the general population, is characterized by limitations in both intellectual function and adaptive skills. The high number of conditions associated with ID underlines its heterogeneous origin and reveals the difficulty of obtaining a rapid and accurate genetic diagnosis. However, the Next Generation Sequencing, and the whole exome sequencing (WES) in particular, has boosted the diagnosis rate associated with ID. In this study, WES performed on 244 trios of patients clinically diagnosed with isolated or syndromic ID and their respective unaffected parents has allowed the identification of the underlying genetic basis of ID in 64 patients, yielding a diagnosis rate of 25.2%. Our results suggest that trio-based WES facilitates ID's genetic diagnosis, particularly in patients who have been extensively waiting for a definitive molecular diagnosis. Moreover, genotypic information from parents provided by trio-based WES enabled the detection of a high percentage (61.5%) of de novo variants inside our cohort. Establishing a quick genetic diagnosis of ID would allow early intervention and better clinical management, thus improving the quality of life of these patients and their families.

科研通智能强力驱动
Strongly Powered by AbleSci AI
科研通是完全免费的文献互助平台,具备全网最快的应助速度,最高的求助完成率。 对每一个文献求助,科研通都将尽心尽力,给求助人一个满意的交代。
实时播报
开放明雪发布了新的文献求助10
1秒前
难过的语儿完成签到,获得积分10
1秒前
1秒前
笨damn完成签到 ,获得积分20
1秒前
1秒前
Atwish完成签到,获得积分10
1秒前
1秒前
lalala发布了新的文献求助10
2秒前
3秒前
byron完成签到,获得积分10
3秒前
一炁发布了新的文献求助10
4秒前
5秒前
素昧平生完成签到,获得积分10
5秒前
郭蕊关注了科研通微信公众号
5秒前
执夏完成签到,获得积分10
5秒前
5秒前
大胆愫发布了新的文献求助10
6秒前
byron发布了新的文献求助200
6秒前
哭泣觅儿完成签到,获得积分20
6秒前
111发布了新的文献求助10
6秒前
思源应助王昊然采纳,获得10
6秒前
7秒前
7秒前
00完成签到,获得积分10
7秒前
7秒前
蚂蚁应助huohup123采纳,获得10
8秒前
阿策完成签到,获得积分10
8秒前
zzz完成签到,获得积分10
8秒前
Flora发布了新的文献求助10
8秒前
8秒前
meiguang完成签到,获得积分20
8秒前
李爱国应助小Z采纳,获得10
9秒前
Atwish发布了新的文献求助10
9秒前
9秒前
慕青应助踏实的谷梦采纳,获得10
9秒前
9秒前
10秒前
Moonpie应助云天河采纳,获得10
11秒前
水波不兴完成签到 ,获得积分10
11秒前
11秒前
高分求助中
(应助此贴封号)【重要!!请各用户(尤其是新用户)详细阅读】【科研通的精品贴汇总】 10000
Autoparametric Resonance in Mechanical Systems 1000
Effects of Two Weeks of Red Light Therapy on Choroidal Thickness and Axial Length in Young Adults 700
Cosmos as Art Object: Studies in Plato's Timaeus and Other Dialogues 600
Management and the Arts 510
Matrix Methods in Data Mining and Pattern Recognition Second Edition 510
Auslegungsgeschichte 500
热门求助领域 (近24小时)
化学 材料科学 医学 生物 纳米技术 工程类 有机化学 化学工程 生物化学 计算机科学 内科学 物理 复合材料 催化作用 细胞生物学 无机化学 光电子学 物理化学 电极 基因
热门帖子
关注 科研通微信公众号,转发送积分 7659771
求助须知:如何正确求助?哪些是违规求助? 9230271
关于积分的说明 19845839
捐赠科研通 7227617
什么是DOI,文献DOI怎么找? 3281506
关于科研通互助平台的介绍 2441230
邀请新用户注册赠送积分活动 2281734