Hip Displacement in Spinal Muscular Atrophy in the Early Disease-Modifying Therapy Era: Association With Hip Pain and Timing of Therapy Initiation

医学 脊髓性肌萎缩 流离失所(心理学) 臀部疼痛 外科 肌电图 萎缩 物理医学与康复 髋关节手术 肌肉萎缩 骨科手术 麻醉 物理疗法 进行性肌萎缩
作者
Sunho Ko,W Kim,Wonik Lee,Sung Eun Hyun,Seungbok Lee,Soo Yeon Kim,Chang Ho Shin,Hyung‐Ik Shin,Tae‐Joon Cho,Jong‐Hee Chae,Mi Hyun Song
出处
期刊:Journal of Pediatric Orthopaedics [Lippincott Williams & Wilkins]
标识
DOI:10.1097/bpo.0000000000003161
摘要

BACKGROUND: Spinal muscular atrophy (SMA) destroys spinal cord anterior horn cells, causing progressive muscle weakness and atrophy. Despite the introduction of disease-modifying therapies (DMTs), their effects on hip displacement remain unclear. This study investigated the development and progression of hip displacement in SMA, with emphasis on the impact of DMTs. METHODS: Patients diagnosed with SMA between 2000 and 2022 who underwent hip surveillance ≥3 times at different ages were included. SMA classification, bilaterality, radiographic parameters, age at DMT initiation, and hip pain were analyzed. Hip displacement was classified by migration percentage. Study-defined early (SDE) DMT use was defined as treatment before 6 months in type 1 SMA or before 2 years in type 2 SMA. RESULTS: Twenty-one patients (10 with type 1 and 11 with type 2 SMA) were included, with a mean follow-up of 31±6 months. In type 1 SMA, 90% of patients developed hip displacement (2 with subluxation and 7 with dislocation), occurring at mean ages of 22.0±7.0 months and 33.0±7.8 months, respectively. In type 2 SMA, 72% of patients developed hip displacement (7 with subluxation and 1 with dislocation), occurring at mean ages of 37.8±16.2 months and 32 months, respectively. SMA classification (P=0.016), bilaterality (P<0.001), presence of hip pain (P=0.006), and final acetabular index (P=0.002) were associated with final hip displacement. SDE DMT use was not statistically significant (P=0.163); however, one type 1 SMA patient who initiated DMT at 1 month maintained a contained hip throughout follow-up. Hip pain was absent in contained or subluxated hips but occurred in 75% of dislocated hips. CONCLUSIONS: Hip displacement in SMA begins early, with progression patterns differing by disease severity. Hip displacement is also associated with pain, which was observed primarily in dislocated hips. These findings highlight the need for routine hip surveillance from early infancy and pain assessment. DMT initiation may confer only minimal benefit when instituted at a later age, but may yield more substantial benefit when administered presymptomatically soon after birth. LEVEL OF EVIDENCE: Level III.
最长约 10秒,即可获得该文献文件

科研通智能强力驱动
Strongly Powered by AbleSci AI
科研通是完全免费的文献互助平台,具备全网最快的应助速度,最高的求助完成率。 对每一个文献求助,科研通都将尽心尽力,给求助人一个满意的交代。
实时播报
霸气若男发布了新的文献求助10
1秒前
认真的博发布了新的文献求助10
2秒前
2秒前
Ava应助百里烬言采纳,获得10
3秒前
英俊的铭应助科研通管家采纳,获得10
3秒前
4秒前
yaoyao6688发布了新的文献求助30
4秒前
深情安青应助科研通管家采纳,获得10
4秒前
科研通AI2S应助科研通管家采纳,获得10
4秒前
美丽涵柏完成签到,获得积分10
4秒前
SnownS发布了新的文献求助20
4秒前
深情安青应助科研通管家采纳,获得10
4秒前
酷波er应助科研通管家采纳,获得30
4秒前
酷波er应助科研通管家采纳,获得10
4秒前
慕青应助科研通管家采纳,获得10
4秒前
4秒前
天天快乐应助科研通管家采纳,获得10
4秒前
33发布了新的文献求助10
5秒前
思源应助琪琪采纳,获得10
5秒前
5秒前
pluto应助科研通管家采纳,获得10
5秒前
搜集达人应助科研通管家采纳,获得10
5秒前
wanci应助科研通管家采纳,获得10
5秒前
小蘑菇应助科研通管家采纳,获得10
5秒前
5秒前
仟111完成签到 ,获得积分10
5秒前
5秒前
我是老大应助科研通管家采纳,获得10
5秒前
5秒前
5秒前
5秒前
无花果应助科研通管家采纳,获得10
5秒前
5秒前
6秒前
6秒前
在水一方应助光轮2000采纳,获得10
7秒前
9秒前
风月难安发布了新的文献求助10
11秒前
琪琪完成签到,获得积分10
11秒前
皖医梁朝伟完成签到 ,获得积分0
12秒前
高分求助中
Principles of Economics, 11th Edition 10000
University Physics with Modern Physics, 16th edition 10000
(应助此贴封号)【重要!!请各用户(尤其是新用户)详细阅读】【科研通的精品贴汇总】 10000
Gründe der Seele:Die Wiener Psychatrie im 20.Jahrhundert 1000
Development of a Bridge Weigh-In-Motion System: A technology to convert the bridge response to the passage of traffic into data on vehicle configurations, speeds, times of travel and weights 1000
Organic Reactions, Volume 116 1000
Current concepts in cutaneous toxicity : proceedings of the Fourth Conference on Cutaneous Toxicity, Washington, D.C., May 9-11, 1979 1000
热门求助领域 (近24小时)
化学 材料科学 医学 生物 纳米技术 工程类 有机化学 化学工程 生物化学 计算机科学 内科学 物理 复合材料 催化作用 细胞生物学 无机化学 光电子学 物理化学 电极 基因
热门帖子
关注 科研通微信公众号,转发送积分 7270747
求助须知:如何正确求助?哪些是违规求助? 8891018
关于积分的说明 18794751
捐赠科研通 6945715
什么是DOI,文献DOI怎么找? 3203779
关于科研通互助平台的介绍 2376656
邀请新用户注册赠送积分活动 2179728