因子V
凝结
复合杂合度
外显子
先证者
突变
遗传学
因子IX
组织因子
分子生物学
基因
蛋白质C
突变体
基因型
生物
组织因子途径抑制剂
基因突变
凝血酶
医学
免疫学
内科学
血小板
生物化学
血栓形成
作者
Shasha Luo,Siqi Liu,Mengjie Xu,Xiaolong Li,Haiyue Zhang,Yanhui Jin,Lihong Yang,Mingshan Wang
标识
DOI:10.1097/mbc.0000000000000946
摘要
To analyze the causative gene and the molecular pathogenesis in a pedigree with compound hereditary coagulation factor V deficiency. Routine blood coagulation indexes and factor V antigen (FV:Ag) were detected by the one-stage clotting method and ELISA. Function of the mutant protein was evaluated by the method Calibrated Automated Thrombogram (CAT). The factor V gene was amplified by PCR with direct sequencing. The possible impact of the mutations were analyzed by bioinformatics tools. The proband's factor V activity and FV:Ag were reduced to 3 and 6%. Gene sequencing revealed compound heterozygous mutations c.911G>A (Gly276Glu) in exon 6 and c.5343C>G (Ser1781Arg) in exon 16. The thrombin generation test showed that the mutant protein markedly decreased thrombin. Bioinformatics indicated that mutations were deleterious. The compound heterozygous mutations Gly276Glu and Ser1781Arg were responsible for the decrease of factor V activity and FV:Ag, of which Ser1781Arg was first reported in the world.
科研通智能强力驱动
Strongly Powered by AbleSci AI