肥厚性心肌病
医学
室间隔
纤维化
肌肉肥大
调解人
细胞生物学
转录因子
发病机制
肌节
旁分泌信号
心肌病
癌症研究
生物信息学
基因
候选基因
心源性猝死
生物
转录组
疾病
病理
内科学
心脏病
信号转导
激活剂(遗传学)
波形蛋白
内分泌学
心肌细胞
猝死
白血病抑制因子受体
肌成纤维细胞
作者
Bowen Lin,Jizheng Wang,Can Li,Shuiyun Wang,Meiting Shen,Lingjie Hu,Lei Chen,Fanhong Zhou,Ying Liu,Jian Yang,Mo Zhang,D Wang,Guoliang Xu,Bin Zhou,Lei Song,Dan Shi,Yi-Han Chen
出处
期刊:Circulation
[Lippincott Williams & Wilkins]
日期:2026-03-16
卷期号:153 (11): 845-862
标识
DOI:10.1161/circulationaha.125.075290
摘要
BACKGROUND: Hypertrophic cardiomyopathy (HCM), the most common inherited cardiac disorder and a leading cause of sudden cardiac death in young adults, exhibits substantial genetic and clinical heterogeneity. Although sarcomere gene sequence variations account for a major proportion of HCM cases, nearly half of patients lack identifiable genetic defects, implying the involvement of undiscovered mechanisms that may converge on a common pathogenic pathway. However, a unified molecular basis underlying HCM pathogenesis remains undefined. METHODS: We conducted an integrated analysis of hypertrophied interventricular septum tissues from 269 patients with obstructive HCM undergoing surgical myectomy. Targeted sarcomere gene screening, bulk RNA sequencing, and weighted gene coexpression network analysis were used to identify candidate drivers of disease. Cross-species validation was performed using a Myh 6 R404Q/+ mouse model. Single-cell RNA sequencing delineated the cellular source of key factors, and biochemical assays and gain- and loss-of-function studies were used to assess their functional relevance. CRLF1 (cytokine receptor-like factor 1) emerged as a candidate mediator and was further evaluated in vitro and in vivo. RESULTS: CRLF1, predominantly secreted by activated cardiac fibroblasts, emerged as a key paracrine factor driving cardiomyocyte hypertrophy across patients with genetically heterogeneous HCM. CRLF1 levels were significantly elevated in hypertrophied myocardium and circulation. CRLF1 activated the LIFR (leukemia inhibitory factor receptor)–JAK1/2 (Janus kinase)–STAT3 (signal transducer and activator of transcription 3) signaling cascade to promote hypertrophy in both murine and human HCM models. Genetic ablation of Crlf1 in fibroblasts or pharmacological inhibition of its downstream pathway markedly attenuated disease phenotypes. CONCLUSIONS: Our findings uncover a common, nongenetic paracrine mechanism underlying HCM pathogenesis and establish CRLF1 as a promising universal therapeutic target for this heterogeneous disease.
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