异质性
线粒体脑肌病
线粒体DNA
症候群
乳酸性酸中毒
肌肉活检
粒线体疾病
线粒体肌病
生物
线粒体脑肌病
突变
遗传学
慢性进行性外眼肌麻痹
病理
基因
医学
活检
内分泌学
作者
Teeratorn Pulkes,L. H. Eunson,Victor Patterson,Asra Tus Saleha Siddiqui,Nicholas Wood,Isabelle Nelson,J A Morgan-Hughes,Michael G. Hanna
标识
DOI:10.1002/1531-8249(199912)46:6<916::aid-ana16>3.0.co;2-r
摘要
We report on 4 male patients with clinical, radiological, and muscle biopsy findings typical of the mitochondrial encephalomyopathy with lactic acidosis and stroke-like episodes (MELAS) phenotype. Skeletal muscle mitochondrial DNA (mtDNA) analysis showed that all patients harbored a heteroplasmic G13513A mutation in the ND5 subunit gene. One of these cases (Patient 1) presented with symptoms characteristic of Leber's hereditary optic neuropathy (LHON) 2 years before the first stroke-like episode. Quantitative analysis in several postmortem tissue sections showed that the relative proportions of mutant mtDNA were generally lower than those reported with other pathogenic mtDNA mutations. Single-fiber polymerase chain reaction studies demonstrated significantly higher amounts of mutant mtDNA in ragged red fibers (RRFs) compared with non-RRFs. This study indicates that the G13513A transition is likely to be pathogenic, that it can cause an LHON/MELAS overlap syndrome, and that it may be a more frequent cause of MELAS than previously recognized.
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